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Birt-Hogg-Dubes syndrom - Förbisett tillstånd som medför ökad risk för njurcancer och pneumotorax
Engelsk titel: Birt-Hogg-Dube syndrome - a neglected condition that increases the risk of kidney cancer and pneumothorax Läs online Författare: Bradley, Maria ; Hedblad, Mari-Anne ; Björck, Erik ; Nordenskjöld, Magnus Språk: Swe Antal referenser: 38 Dokumenttyp: Översikt UI-nummer: 11127734

Tidskrift

Läkartidningen 2011;108(50)2657-9 ISSN 0023-7205 E-ISSN 1652-7518 KIBs bestånd av denna tidskrift Denna tidskrift är expertgranskad (Peer-Reviewed)

Sammanfattning

Birt–Hogg–Dubés syndrome (BHD) is an autosomal dominant disease characterized by fibrofolliculomas, spontaneous pneumothorax and renal cancer. It was first described in 1977, and in 2002 mutations in the FLCN gene were identified as the cause of the disease. The gene encodes the protein folliculin whose function is largely unknown but has been linked to mTOR pathway. It is important to identify individuals with a FLCN mutation in order to include them in a screening program for early detection and treatment of renal cancer. For the medical profession it is important to recognize the typical skin lesions (fibrofolliculomas) of BHD and to consider the syndrome in families with several cases of renal cancer and/or spontaneous pneumothorax.